Congenital prepubic sinus: A case report and review of the literature

•Congenital prepubic sinus presents most often in infancy with purulent discharge.•Anatomical and pathological features often differ from each case.•Preoperative MRI was useful for complete excision of a sinus tract.

Congenital prepubic sinus (CPS) is an extremely rare anomaly, which is often associated with purulent discharge from a midline opening overlying the pubis. CPS was first described by Campbell et al. in 1987 and they suggested that it might represent a variation in normal embryological development. Several theories have been proposed regarding the pathogenesis of CPS. However, the etiology of CPS is still unclear because the anatomical and pathological features of CPS often differ from each other. We report a case of CPS and review the literature to improve the global understanding of CPS.