Congenital bifid tongue with lingual hamartoma: A case report and review of the literature

A non-syndromic, congenital bifid tongue is an extremely rare malformation, the details of which are largely unknown. A female neonate was referred to our division presenting with a bifid tongue. The cleft was located in the right anterior part of the tongue. In addition, 2 tumors (10 mm and 2 mm) were located at the base of the cleft. Seven days after birth, the tumors were excised and primary closure of the cleft was performed for correction of the bifid tongue. The postoperative course was uneventful, and follow-up examination 20 months later showed no functional disturbance. Furthermore, all published cases were carefully reviewed to improve our understanding of the etiology of congenital bifid tongue. Formation of a congenital neoplasm during the early stages of tongue development could be the main etiology of a bifid tongue.