Giant keratocystic odontogenic tumor invading bilateral maxillary sinuses

A 40-year-old female presented at our hospital with swelling of the left cheek. Computed tomography showed a benign tumor that filled the bilateral maxillary sinuses and was compressing and absorbing the inferior nasal meatus. The clinical diagnosis was a maxillary odontogenic benign tumor, such as a calcifying cystic odontogenic tumor. A biopsy was performed and the pathology examination revealed a diagnosis of KCOT. In determining the treatment plan, cosmetic considerations were required. We performed marsupialization and observed shrinkage of the tumor, in line with previous reports. We then performed enucleation under the guidance of a rigid endoscope through the oral cavity. To date, there has been no recurrence and the progress is good. However, this disease has a high recurrence rate and must be carefully observed.